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Bilateral congenital choanal atresia and osteoma of ethmoid sinus with supernumerary nostril: a case report and review of the literature.

Li XZ, Cai XL, Zhang L, Han XF, Wei X - J Med Case Rep (2011)

Bottom Line: A 22-year-old Chinese man presented with mouth breathing, sleep snoring and difficult feeding after birth, with no olfactory sensation.Three-dimensional computed tomography revealed bilateral choanal atresia and a high density bony shadow in his left ethmoid sinus that extended to his left frontal sinus.To the best of our knowledge, this is the first report of choanal atresia accompanied by congenital accessory nasal deformity and congenital keratoleukoma.

View Article: PubMed Central - HTML - PubMed

Affiliation: Department of Otolaryngology, Qilu Hospital, Shandong University, Ji'nan 250012, China. zhangleicome@126.com.

ABSTRACT

Introduction: Congenital choanal atresia is a relatively rare deformity, especially bilateral congenital choanal atresia. We report a case of bilateral congenital choanal atresia in a 22-year-old Chinese man, who was also diagnosed with congenital right accessory nasal deformity, osteoma of his left ethmoid sinus and congenital keratoleukoma of his right eye.

Case presentation: A 22-year-old Chinese man presented with mouth breathing, sleep snoring and difficult feeding after birth, with no olfactory sensation. Three-dimensional computed tomography revealed bilateral choanal atresia and a high density bony shadow in his left ethmoid sinus that extended to his left frontal sinus.

Conclusions: Choanal atresia is often accompanied by other congenital abnormalities. To the best of our knowledge, this is the first report of choanal atresia accompanied by congenital accessory nasal deformity and congenital keratoleukoma.

No MeSH data available.


Related in: MedlinePlus

Ethmoid sinus postoperation. Re-examination three months after the operation.
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Figure 10: Ethmoid sinus postoperation. Re-examination three months after the operation.

Mentions: A soft and elastic membrane was found to block both posterior nares. A cruciate incision was made in the membrane center and the openings were widened to the bony part of the posterior nares. A silica gel about 0.8 cm in diameter and 7 cm in length, with multiple holes in the lateral wall, was placed bilaterally from anterior to posterior nares to prevent re-stenosis. The silica gel was removed six weeks later. After more than three years of follow-up, both anterior and posterior nares were capacious and nasal ventilation was normal (Figures 9 and 10). Olfactory function recovered partially. Closed rhinolalia and sleep snoring were all remarkably relieved.


Bilateral congenital choanal atresia and osteoma of ethmoid sinus with supernumerary nostril: a case report and review of the literature.

Li XZ, Cai XL, Zhang L, Han XF, Wei X - J Med Case Rep (2011)

Ethmoid sinus postoperation. Re-examination three months after the operation.
© Copyright Policy - open-access
Related In: Results  -  Collection

License
Show All Figures
getmorefigures.php?uid=PMC3285051&req=5

Figure 10: Ethmoid sinus postoperation. Re-examination three months after the operation.
Mentions: A soft and elastic membrane was found to block both posterior nares. A cruciate incision was made in the membrane center and the openings were widened to the bony part of the posterior nares. A silica gel about 0.8 cm in diameter and 7 cm in length, with multiple holes in the lateral wall, was placed bilaterally from anterior to posterior nares to prevent re-stenosis. The silica gel was removed six weeks later. After more than three years of follow-up, both anterior and posterior nares were capacious and nasal ventilation was normal (Figures 9 and 10). Olfactory function recovered partially. Closed rhinolalia and sleep snoring were all remarkably relieved.

Bottom Line: A 22-year-old Chinese man presented with mouth breathing, sleep snoring and difficult feeding after birth, with no olfactory sensation.Three-dimensional computed tomography revealed bilateral choanal atresia and a high density bony shadow in his left ethmoid sinus that extended to his left frontal sinus.To the best of our knowledge, this is the first report of choanal atresia accompanied by congenital accessory nasal deformity and congenital keratoleukoma.

View Article: PubMed Central - HTML - PubMed

Affiliation: Department of Otolaryngology, Qilu Hospital, Shandong University, Ji'nan 250012, China. zhangleicome@126.com.

ABSTRACT

Introduction: Congenital choanal atresia is a relatively rare deformity, especially bilateral congenital choanal atresia. We report a case of bilateral congenital choanal atresia in a 22-year-old Chinese man, who was also diagnosed with congenital right accessory nasal deformity, osteoma of his left ethmoid sinus and congenital keratoleukoma of his right eye.

Case presentation: A 22-year-old Chinese man presented with mouth breathing, sleep snoring and difficult feeding after birth, with no olfactory sensation. Three-dimensional computed tomography revealed bilateral choanal atresia and a high density bony shadow in his left ethmoid sinus that extended to his left frontal sinus.

Conclusions: Choanal atresia is often accompanied by other congenital abnormalities. To the best of our knowledge, this is the first report of choanal atresia accompanied by congenital accessory nasal deformity and congenital keratoleukoma.

No MeSH data available.


Related in: MedlinePlus